Case Report

Adrenal Cavernous Hemangioma: A Rarely Perceived Pathology—Case Illustration and Review of Literature

Table 1

List of all published cases of adrenal cavernous hemangiomas.

Case numberAuthors (year of publication)Age/genderLateralitySize (cm)PresentationSurgery

1Johnson and Jeppesen (1955) [3]46/FRight6.5  4  3HypertensionOpen right adrenalectomy
2Elliot et al. (1963) [5]37/FLeft25Incidental findingOpen left adrenalectomy
3Chodof et al. (1966) [6]76/FLeft18  16Abdominal mass and discomfortOpen left adrenalectomy
4Weiss and Schulte (1966) [7]70 /MRight11  7  6Acute urinary retention (−ve met)Open right adrenalectomy
5Ruebel (1973) [8]75/MRight8  7.3  6.5HematuriaOpen right adrenalectomy
6Rothberg et al. (1978) [9]72`/FRight14  10  7Long standing hypertensionOpen right adrenalectomy
7Rothberg et al. (1978) [9]74/FLeft9  8Incidental findingOpen left adrenalectomy
8Vargas (1980) [10]67/FLeftNAIncidental finding on barium study for chronic anemiaOpen left adrenalectomy
9Lee et al. (1982) [11]59/FRight8.5  7  6Incidental abdominal calcificationOpen right adrenalectomy
10Orringer et al. (1983) [4]51/MRight17Epigastric heavinessExploratory laparotomy with adrenalectomy
11Goren et al. (1986) [12]79/FRight9  7  5Incidental finding (−ve metab)Open right adrenalectomy
12Nakagawa et al. (1986) [13]71/MLeft10  18  24Night sweat and generalised fatigueOpen left adrenalectomy
13Guerin et al. (1988) [14]78/FLeft3  2.5  2.5Elevated ESROpen left adrenalectomy
14Derchi et al. (1989) [15]69/FLeft20Incidental findingOpen left adrenalectomy
15Derchi et al. (1989) [15]60/MRight18Hepatomegaly and abdominal painOpen right adrenalectomy
16Yoshihirio et al. (1990) [16]78/FLeft6  5.5  5Incidental findingOpen left adrenallectomy
17Honig et al. (1991) [17]73/MLeftNAIncidental findingExprolatory laparotomy with adrenalectomy
18Takahe et al. (1991) [18]55/MLeft10  9  9Incidental findingOpen left adrenalectomy with splenectomy
19Salup et al. (1992) [19]73/FLeft15Syncope (incidental finding)Open left adrenalectomy,distal pancreatectomy, splenectomy and left radical nephrectomy
20Hamrick et al. (1993) [20]66/Mleft9Incidental findingOpen adrenalectomy
21Sabanegh et al. (1993) [21]60/Fleft20  20Incidental findingOpen left adrenalectomy
22Boraschi et al. (1995) [22]64/Mright10  8  6.5Megaloblastic anemiaOpen adrenalectomy
23Stumvoll et al. (1996) [23]60/FRight8Mineralocorticoid excess syndromeOpen partial right adrenalectomy
24Marotti et al. (1997) [24]68/FLeft14  10  10Incidental findingOpen adrenalectomy
25Marotti et al. (1997) [24]60/FLeft9  7.5  5Incidental findingOpen adrenalectomy
26Oh et al. (1997) [25]56/MRight6  5  4Right flank discomfortOpen right adrenalectomy
27Hayakawa et al. (1998) [26]56/MLeft5Incidental findingOpen left adrenalectomy
28Hisham et al. (1998) [27]61/FRight25Flank painOpen right adrenalectomy
29Makiyama et al. (1998) [28]61/FRight5.5  3.5  3.5Incidental findingOpen right adrenalectomy
30Thiele and Bodie (2001) [29]72/FLeft9.5  4.2  4.5Incidental findingOpen left adrenalectomy
31Yagisawa et al. (2001) [30]52/MRight6.5  7Dull back painLaparoscopic right adrenalectomy
32Xu and Liu (2002) [31]60/MRight17Abdominal mass incidental findingOpen right adrenalectomy
33Nursal et al. (2004) [32]48/FLeft13Palpitation and unremitting hypertensionLaparotomy with left adrenalectomy
34Wang et al. (2004) [33]63/FLeft5.5  5  4Left upper quadrant painLeft adrenalectomy
35Forbes (2005) [34]75/MLeft19  18  8Retroperitoneal hemorrhageLaparotomy
36Heis et al. (2008) [35]50/FRight10Flank painOpen right adrenalectomy
37Ng et al. (2008) [36]59/MLeft3.1  2.9Incidental finding (primary hyperaldosteronism)Laparoscopic left adrenalectomy
38Nigri et al. (2008) [37]58/FRight7  4.5  3Incidental findingLaparoscopic right adrenalectomy
39Arkadopoulos et al. (2009) [38]75/FLeft8  6  4Incidental findingOpen left adrenalectomy
40Matsuda et al. (2009) [39]51/MLeft4  4  3.5Incidental findingLaparoscopic left adrenalectomy
41Siddiqi et al. (2009) [40]54/FRight2.8  2.5Abdominal painNA
42Telem et al. (2009) [41]42/FLeft12Left flank painLaparoscopic left adrenalectomy q
43Cheong and Kim (2010) [42]66/FLeft4.5  3.4Incidental findingLaparoscopic left adrenalectomy
44Paluszkieweicz et al. (2010) [43]45/MLeftNARetroperitoneal hemorrhageLaparotomy
45Abu EL Ghar et al. (2011) [44]44/MRight11  6Incidental findingNA
46Al Jabri et al. (2011) [45]19/FRight4.3  7.3  5.4Incidental findingLaparoscopic right adrenalectomy
47kieger et al. (2011) [46]53/FRight2Microscopic hematuriaNo surgical management
48Oishi et al. (2012) [47]75/FLeft5  5  3Incidental finding with positive metabolic workup for subclinical cushing diseaseOpen adrenalectomy
49Quildrian et al. (2012) [48]62/FLeft12.5  11.5  8Incidental findingOpen left adrenalectomy
50Edward et al. (2013) [49]78/FRight5.4  3.3Incidental findingLaparoscopic right adrenalectomy
51Galea et al. (2013) [50]84/FLeft13  11Flank painOpen left adrenalectomy
52Noh et al. (2014) [51]27/FRight7.8  7.8Incidental findingLaparoscopic right adrenalectomy
53Wang et al. (2014) [52]37/MRight6  5  4.5Incidental findingLaparoscopic right adrenalectomy
54Agrusa et al. (2015) [53]49/FRight11  7.5  7Nonspecific abdominal symptoms (epigastric pain, nausea and vomiting)Laparoscopic right adrenalectomy
55Wong et al. (2015) [54]80/FRight12.3  13.9  13.8Incidental findingLaparotomy and right adrenalectomy
56Pang et al. (2015) [55]71/FLeft9.5  8  7.5Chronic abdominal distentionLaparoscopic left adrenalectomy
57Tarchouli et al. (2015) [56]71/FRight42  38  17Intermittent abdominal pain and increase abdominal girthLaparotomy and open adrenalectomy
58Bacha et al. (2016) [57]60/MLeft17.5  17  9Incidental findingOpen adrenalectomy
59Kinebuchi et al. (2016) [58]77/MLeft5.4  4.3Incidental findingLaparoscopic adrenalectomy
60Njoumi et al. (2017) [59]30/FRight7Incidental findingLaparoscopic right adrenalectomy
61Tadic et al. (2017) [60]50/FRight11.5  11  11Intermittent flank pain and abdominal discomfortOpen right adrenalectomy
62Feo et al. (2018) [61]70/MLeft9  6.5  7Incidental findingOpen left adrenalectomy
63Hashimoto et al. (2018) [62]70/MLeft27  17  5.5Loss of appetiteLaparoscopic left adrenalectomy
64Iwamot et al. (2018) [63]52/MLeft5  3.7  3Incidental findingAdreno-nephrectomy
65Lavingia et al. (2018) [64]64/MRight64  5.5  4.7Incidental findingOpen right adrenalectomy
66Peng et al. (2018) [65]31/FRightNARight upper quadrant and flank painLaparotomy and adrenalectomy